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New lethal skeletal dysplasia with Dandy–Walker malformation, congenital heart defects, abnormal thumbs, hypoplastic genitalia, and distinctive facies

✍ Scribed by Cathy A. Stevens; Ralph S. Lachman


Publisher
John Wiley and Sons
Year
2010
Tongue
English
Weight
264 KB
Volume
152A
Category
Article
ISSN
1552-4825

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✦ Synopsis


Abstract

We report on two sibs with a lethal form of bone dysplasia with distinctive skeletal findings including rhizomelic and mesomelic limb shortening, hooked clavicles, dumbbell femurs, and absence of talus and calcaneus ossification. Other clinical features include Dandy–Walker malformation, congenital heart defects, joint contractures, genital hypoplasia, and distinctive facial features. These sibs appear to have a previously undescribed skeletal dysplasia, which is most likely inherited in an autosomal recessive fashion. © 2010 Wiley‐Liss, Inc.