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Arg(184)his mutant GTP cyclohydrolase I, causing recessive hyperphenylalaninemia, is responsible for dopa-responsive dystonia with parkinsonism: A case report

✍ Scribed by Akio Kikuchi; Atsushi Takeda; Kazuo Fujihara; Teiko Kimpara; Yusei Shiga; Hiroaki Tanji; Makiko Nagai; Hiroshi Ichinose; Fumi Urano; Nobuyuki Okamura; Hiroyuki Arai; Yasuto Itoyama


Book ID
102945024
Publisher
John Wiley and Sons
Year
2004
Tongue
English
Weight
514 KB
Volume
19
Category
Article
ISSN
0885-3185

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✦ Synopsis


Abstract

We describe a 54‐year‐old man with dominant adult‐onset dopa‐responsive dystonia (DRD) with parkinsonism caused by an Arg184His mutation in guanosine 5′‐triphosphate cyclohydrolase I (GCH‐I). This is the first mutation in the GCH‐I gene that has been proven to be responsible for both recessive and dominant phenotypes. © 2004 Movement Disorder Society